We report a case of hypoplastic gallbladder associated choledocholithiasis. A 62 year-old woman with Symptom-Free liver dysfunction was found by abdominal ultrasonography to have choledocholithiasis and referred to our hospital for surgery. On admission to the hospital, laboratory data were within the normal range. Drip infusion cholangiography showed dilatation of the common bile duct and choledocholithiasis. The gallbladder could not be seen clearly. Abdominal computed tomography (CT) showed no problem but was stillunable to picture the gallbladder. We operated under a diagnosis of choledocholithiasis and atrophic cholecystitis. The gallbladder was hypoplastic, and we conducted cholecystectomy and choledocholithotomy. A congenital absence of the gallbladder or a hypoplastic gallbladder are relatively rare, but should be considered, if the gallbladder cannot be seen.