Elsevier

Surgical Neurology

Volume 67, Issue 2, February 2007, Pages 207-210
Surgical Neurology

Infection
Medically treated paravertebral Brucella abscess presenting with acute torticollis: case report

https://doi.org/10.1016/j.surneu.2006.06.061Get rights and content

Abstract

Background

Atlantoaxial subluxation secondary to a paravertebral (retropharyngeal) abscess is a well known but rare event in children.

Case Description

The authors describe the clinical and radiologic findings of a case of 6-year-old child who presented with acute torticollis (duration, 4 days). Type 2 atlantoaxial rotatory fixation and upper cervical paravertebral (retropharyngeal) abscess were diagnosed on radiologic examination. Laboratory test results showed positive agglutination titer for Brucella melitensis, in the rate of 1/640 dilution. This is the first reported case of Brucella-related atlantoaxial subluxation in a child in the pediatric literature. The patient was treated successfully with anti-inflammatory drugs, Brucella-specific antibiotic regimen, and Philadelphia collar application. Possibly, effusion of the atlantoaxial joint, due to Brucella infection, led to the laxity of the ligaments and contributed to subluxation.

Conclusions

Brucella abscess should be kept in mind for the differential diagnosis of retropharyngeal mass, and the torticollis may be the only presenting sign. The authors recommend a trial of medical treatment with adequate dosages for a reasonable length of time and immobilization before considering surgical intervention for the spinal paravertebral Brucella abscess and related atlantoaxial subluxation.

Introduction

Atlantoaxial rotatory subluxation is rather an uncommon entity in which the main feature is either subluxation or dislocation of the atlas on the axis [7], [8], [20]. It is typically seen in children following otolaryngeal entities such as pharyngitis, nasopharyngitis, adenotonsillitis, tonsillar abscess, parotitis, cervical abscess, and otitis media [2], [5], [7], [8], [12], [13], [22], [24]. This deformity needs individualized treatment modalities depending upon radiologic grade, timing of the diagnosis, and the etiology.

Here the authors present a case with acute torticollis. On initial radiographs, type 2 AARS was diagnosed. Cervical MRI of the patient revealed paravertebral (retropharyngeal) abscess from C1 through C5, which was caused by Brucella. This is a unique case of upper cervical brucellosis, diagnosed while searching for the differential diagnosis of AARS.

Section snippets

Case report

A 6-year-old boy presented with a painful and stiff neck that started suddenly 4 days previously. He had no history of trauma. At physical examination, his head rotated to the left with the chin tilted to the right (cock-robin). Neck movement was restricted and painful in the direction of the deformity. His neurologic examination was normal. Plain radiograms showed an increased and subluxation of C1 over C2. Atlantoaxial rotatory subluxation was confirmed with CT of the atlantoaxial joint and

Discussion

Atlantoaxial rotatory subluxation is usually seen in children, following otitis media, pharyngitis, viral infections, retropharyngeal abscess, tonsillectomy, pharyngoplasty, retropharyngeal inflammation, or minor trauma, and some of them with unknown etiology [2], [5], [7], [8], [12], [13], [22], [24]. In the pediatric age group, atlantoaxial subluxation secondary to retropharyngeal abscess is a well described but rare event. However, to our best of knowledge, no case has been reported

Conclusions

Patients with torticollis who had AARS should not be underestimated. The most important point is that delayed diagnosis affects the prognosis and treatment protocol and is a major cause of recurrence and instability on AARS. Brucellosis should be kept in mind as the etiology of upper cervical paravertebral abscess. The authors recommend a trial of medical treatment with adequate dosages for a reasonable length of time and immobilization before considering surgical intervention in spinal

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    This case was first reported at the 13th World Congress of Neurological Surgery in Marrakech, Morocco, 2005.

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