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A rare cause of dyspnea due to chylothorax

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Abstract

We report the case of an 8-year-old boy who presented to the emergency department of another hospital and was referred to our pediatric intensive care unit with dyspnea and tachypnea of recent onset. The diagnosis of massive chylothorax with mediastinal shift was made on chest radiographs and CT scan. Initial investigations revealed no definite cause for the chylothorax. On later radiography and CT imaging with 3D surface rendering, a marked bone loss of the left ribs, clavicle, and shoulder joint was shown. The diagnosis of Gorham–Stout disease associated with chylothorax was suspected and histologically confirmed.

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References

  1. Patel DV (2004) Gorham’s disease or massive osteolysis. Clin Med Res 3:65–74

    Article  Google Scholar 

  2. Riantawan P, Tansupasawasdikul S, Subhannachart P (1996) Bilateral chylothorax complicating massive osteolysis (Gorham’s syndrome). Thorax 51:1277–1278

    Article  CAS  PubMed  Google Scholar 

  3. Patrick JH (1976) Massive osteolysis complicated by chylothorax successfully treated by pleurodesis. J Bone Joint Surg 58B:347–349

    Google Scholar 

  4. Resnick D (2002) Chapter 89. Osteolysis and chondrolysis. In: Resnick D (ed) Diagnosis of bone and joint disorders, 4th edn. Saunders, Philadelphia, pp 4920–4944

    Google Scholar 

  5. Kai B, Ryan A, Munk PL, Dunllop P (2006) Gorham disease of bone: three cases and review of radiological features. Clin Radiol 61:1058–1064

    Article  CAS  PubMed  Google Scholar 

  6. Duffy BM, Manon R, Patel RR, Welsh JS (2004) A case of Gorham’s disease with chylothorax treated curatively with radiation therapy. Clin Med Res 3:83–86

    Article  Google Scholar 

  7. Hammer F, Kenn W, Wesselmann U, Hofbauer LC, Delling G, Allolio B, Arlt W (2005) Gorham–Stout disease-stabilization during biphosphonate treatment. J Bone Miner Res 20:350–353

    Article  PubMed  Google Scholar 

  8. Hagberg H, Lamberg K, Astrom G (1997) A-2b Interferon and oral clodronate for Gorham’s disease. Lancet 350:1822–1823

    Article  CAS  PubMed  Google Scholar 

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Correspondence to Michel De Maeseneer.

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De Smet, K., De Maeseneer, M., Huijssen-Huisman, E. et al. A rare cause of dyspnea due to chylothorax. Emerg Radiol 17, 503–505 (2010). https://doi.org/10.1007/s10140-010-0898-3

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  • DOI: https://doi.org/10.1007/s10140-010-0898-3

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