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Pyostomatitis vegetans in childhood

  • Infectious Disease
  • Published:
European Journal of Pediatrics Aims and scope Submit manuscript

Abstract

Pyostomatitis vegetans is an oral eruption, characterized by small pustules, ulcers and erythematous vegetations of the labial and buccal mucosae as well as labial-attached gingivae. Its importance lies in its high correlation with inflammatory bowel disease. It is commonly associated with skin and inflammatory bowel disease and is rare in children. We here report a sister and brother with onset of the disease at the age of 5 and 7 years, respectively. It is the first report of familial pyostomatitis vegetans occurring in the youngest patients hitherto reported.

Conclusion

The observation of two sibs with pyostomatitis, vegetans pyoderma gang-renosum and inflammatory bowel disease suggest a hereditary disposition to this rare triad.

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Abbreviations

IBD:

inflammatory bowel disease

PG:

pyoderma gangrenosum

PV:

pyostomatitis vegetans

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Authors and Affiliations

  1. Paediatric Department, Jordan University of Science and Technology, P.O. Box 3030, Irbid-Jordan

    H. S. Al-Rimawi

  2. Periodontal department, Jordan University of Science and Technology, Irbid-Jordan

    M. M. Hammad

  3. Pathology Department, Jordan University of Science and Technology, Irbid-Jordan

    E. A. Raweily & H. M. Hammad

Authors
  1. H. S. Al-Rimawi
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  2. M. M. Hammad
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  3. E. A. Raweily
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  4. H. M. Hammad
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Al-Rimawi, H.S., Hammad, M.M., Raweily, E.A. et al. Pyostomatitis vegetans in childhood. Eur J Pediatr 157, 402–405 (1998). https://doi.org/10.1007/s004310050838

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  • DOI: https://doi.org/10.1007/s004310050838

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